About a case of laryngeal location of SAPHO

Copyright © 2017 Société Nationale Française de Médecine Interne (SNFMI). Published by Elsevier SAS. All rights reserved..

INTRODUCTION: Synovitis, acne, pustulosis, hyperostosis, osteitis (SAPHO) is a syndrome that combines dermatological, articular and osseous inflammatory manifestations. Bilateral laryngeal immobility relative to cricoarytenoid joint origin is very uncommon. This article presents a case of bilateral cricoarytenoid joint ankylosis in a SAPHO syndrome context.

CASE REPORT: A 53-year-old patient presenting with a two year history of intermittent bouts of dyspnea. A SAPHO syndrome was discussed on repeated thoracic CT-scan. The link between dyspnea and SAPHO syndrome had not been made immediately given the absence of any known anteriority. However, having ruled out other etiologies and after having had to perform a tracheotomy due a worsening of the respiratory condition, this diagnosis was considered. Treatment by corticosteroids and infliximab permitted a clinical improvement of the patient.

CONCLUSION: This clinical case report should increase awareness of possible cricoarytenoid joint involvement in SAPHO.

Medienart:

E-Artikel

Erscheinungsjahr:

2017

Erschienen:

2017

Enthalten in:

Zur Gesamtaufnahme - volume:38

Enthalten in:

La Revue de medecine interne - 38(2017), 10 vom: 21. Okt., Seite 700-703

Sprache:

Französisch

Weiterer Titel:

À propos d’un cas de SAPHO de localisation laryngée

Beteiligte Personen:

Vatin, L [VerfasserIn]
Jean, E [VerfasserIn]
Rivière, D [VerfasserIn]
Montava, M [VerfasserIn]
Giovanni, A [VerfasserIn]
Dessi, P [VerfasserIn]
Lagier, A [VerfasserIn]

Links:

Volltext

Themen:

Atteinte laryngée
Case Reports
Dyspnée
Dyspnea
Journal Article
Laryngeal involvement
SAPHO syndrome
Syndrome SAPHO

Anmerkungen:

Date Completed 31.10.2017

Date Revised 31.10.2017

published: Print-Electronic

Citation Status MEDLINE

doi:

10.1016/j.revmed.2017.02.005

funding:

Förderinstitution / Projekttitel:

PPN (Katalog-ID):

NLM270102159